Background: Hair-thread tourniquet syndrome (HTTS) is a rare condition and it refers to the strangulation of a distal appendage by thread or hair, leading to impairment of blood flow and ischemia which if left untreated becomes a surgical emergency. It is usually misdiagnosed due to its infrequent presentation in a hidden part of the body. Case Presentation: A-3-months-old-female infant presented to a governmental institute with a history of irritability, restlessness, and continuous crying without an obvious cause. The diagnosis of HTTS was made as the third digit of the left foot was swollen and red. A surgical incision was made, and hair tourniquet was removed. The follow-up had satisfactory results. Conclusion: HTTS is a rare condition and it is vital to recognize it and provide immediate treatment. Delay of treating this medical issue can lead to strangulation of a distal appendage which may lead to impairments of blood flow and ischemia.

Keywords: Hair thread tourniquet syndrome, HTTS, hair tourniquet management, hair tourniquet removal, irritable infant, restless infant.